Nagashima, Yoji
   Department   School of Medicine(Tokyo Women's Medical University Hospital), School of Medicine
   Position   Professor and Division head
Article types Case report
Language English
Peer review Non peer reviewed
Title Multiple intestinal lymphangiomas with episodic hemorrhage requiring partial laparoscopic resection: a case report.
Journal Formal name:Surgical case reports
Abbreviation:Surg Case Rep
ISSN code:21987793/21987793
Domestic / ForeginForegin
Volume, Issue, Page 8(1),pp.56
Author and coauthor KONDO Hiroka, OHKI Takeshi, OGAWA Shimpei, OMORI Teppei, ONIZUKA HiHiromi, Nagashima, Yoji, YAMAGUCHI SHIGEKI
Publication date 2022/03
Summary BACKGROUND:Lymphangioma is a non-epithelial tumor marked by aggregates of abnormally dilated lymphatics. Mesenteric occurrences account for < 1% of all cases, and < 0.05% involve the gastrointestinal tract. Most are confined to children, rarely affecting adults.CASE PRESENTATION:Herein, we describe an elderly Japanese woman with anemia, hypoalbuminemia, and episodic bleeding due to multiple intestinal lymphangiomas. Abdominal computed tomography revealed multiple low-density defects of mesentery, with areas of intermediate (T1 images) or high (T2 images) signal intensity similarly dispersed in magnetic resonance scanning sequences. Single-balloon enteroscopy was undertaken, enabling identification and tattooing of a small intestinal bleeding source. Laparoscopy-assisted resection at this site served to control related hemorrhage, removing a histologically confirmed hemolymphangioma. Having recovered uneventfully, the patient remained stable 2 months postoperatively.CONCLUSIONS:Although rare in adults, mesenteric or gastrointestinal lymphangiomas must be considered in a setting of anemia and hypoalbuminemia. Complete resection is advantageous to improve patient symptoms, but limited resection of multiple lesions may be equally effective.
DOI 10.1186/s40792-022-01411-y
PMID 35357631